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CANDLE syndrome

"CANDLE" stands for chronic atypical neutrophilic dermatosis with lipodystrophy and elevated temperature. The most common symptoms are fevers, fat loss, and skin lesions

Prevalence

1-9 / 100 000

Ultra-rare

US Estimated

Ultra-rare

Europe Estimated

Age of Onset

Infancy

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ICD-10

M04.8

D89.8

Inheritance Pattern

Autosomal dominant

no https://raremedicalnews.com/wp-content/uploads/2024/02/Depositphotos_61309421_L.jpg

Autosomal recessive

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Mitochondrial/Multigenic

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X-linked dominant

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X-linked recessive

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Rare View

CANDLE syndrome is a proteasome-associated autoinflammatory interferonopathy (PRAAS) presenting in infancy with recurrent fevers, neutrophilic dermatosis-like skin lesions, progressive lipodystrophy, and systemic inflammation. It is linked to pathogenic variants in proteasome-related genes (e.g., PSMB8, others) and is characterized by chronic inflammatory burden and growth failure. Diagnosis is clinical plus inflammatory labs/biopsy patterns and is confirmed by molecular testing; recognition matters because JAK inhibition can significantly improve disease control.

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5 Facts you should know

FACT

1

CANDLE Syndrome (Chronic Atypical Neutrophilic Dermatosis with Lipodystrophy and Elevated temperature) is an autoinflammatory disorder characterized by early-onset recurrent fevers, skin lesions, lipodystrophy, and systemic inflammation

FACT

2

It typically begins in early childhood, with symptoms including persistent fevers, joint stiffness, skin rashes, and progressive loss of subcutaneous fat, leading to a distinctive facial appearance and body shape

FACT

3

CANDLE Syndrome is caused by mutations in genes involved in the regulation of type I interferon signaling, contributing to the activation of the immune system and chronic inflammation

FACT

4

Diagnosis involves clinical evaluation, skin biopsies to identify specific histopathological changes, and genetic testing to confirm mutations related to interferonopathies

FACT

5

Treatment aims to manage symptoms and reduce inflammation using corticosteroids, disease-modifying antirheumatic drugs (DMARDs), and biologic agents targeting the overactive immune response

CANDLE syndrome is also known as...

CANDLE syndrome is also known as:

  • Chronic atypical neutrophilic dermatosis with lipodystrophy and elevated temperature

What’s your Rare IQ?

CANDLE syndrome, a rare autoinflammatory disorder, is characterized by chronic inflammation and lipodystrophy. What does CANDLE stand for?

Common signs & symptoms

Recurrent or persistent fevers starting early in life

Painful violaceous plaques/nodules; neutrophilic dermatosis-like eruptions

Progressive lipodystrophy (partial/generalized), failure to thrive

Arthralgia/arthritis; myositis features in some

Hepatosplenomegaly/lymphadenopathy may occur

Chronic inflammation labs (CRP/ESR elevated); interferon signature in many cases

Complications from chronic inflammation (growth delay, organ involvement)

Current treatments

Glucocorticoids may help short-term but toxicity limits long-term use

Conventional biologics (IL-1/TNF/IL-6 blockade) may be incomplete/temporary in many reports

JAK inhibitors (e.g., baricitinib) have shown meaningful clinical benefit in published experience and ongoing research

Specialist-directed multidisciplinary care: infection surveillance, metabolic/nutritional support, growth monitoring

Pharma tie-ins (possible): Eli Lilly (baricitinib), other JAK inhibitor manufacturers (class effect; off-label in many regions)

References:

  1. Boyadzhiev M, et al. Disease course and treatment effects of a JAK inhibitor in CANDLE (and related interferonopathies). 2019.
  2. Gedik KC, et al. Baricitinib exposure–response and disease flares in CANDLE/PRAAS. Ann Rheum Dis. 2024.
  3. McDermott A, et al. Proteasome-associated autoinflammatory syndrome / CANDLE discussion incl. JAK inhibitor rationale. 2013.